Comprehensive analysis and ACMG-based classification ofCHEK2variants in hereditary cancer patients


Por: Vargas-Parra, G, del Valle, J, Rofes, P, Gausachs, M, Stradella, A, Moreno-Cabrera, JM, Velasco, A, Tornero, E, Menendez, M, Munoz, X, Iglesias, S, Lopez-Doriga, A, Azuara, D, Campos, O, Cuesta, R, Darder, E, de Cid, R, Gonzalez, S, Teule, A, Navarro, M, Brunet, J, Capella, G, Pineda, M, Feliubadalo, L and Lazaro, C

Publicada: 1 dic 2020 Ahead of Print: 1 oct 2020
Resumen:
CHEK2variants are associated with intermediate breast cancer risk, among other cancers. We aimed to comprehensively describeCHEK2variants in a Spanish hereditary cancer (HC) cohort and adjust the American College of Medical Genetics and Genomics and the Association for Molecular Pathology (ACMG-AMP) guidelines for their classification. First, threeCHEK2frequent variants were screened in a retrospective Hereditary Breast and Ovarian Cancer cohort of 516 patients. After, the wholeCHEK2coding region was analyzed by next-generation sequencing in 1848 prospective patients with HC suspicion. We refined ACMG-AMP criteria and applied different combined rules to classifyCHEK2variants and define risk alleles. We identified 10CHEK2null variants, 6 missense variants with discordant interpretation in ClinVar database, and 35 additional variants of unknown significance. Twelve variants were classified as (likely)-pathogenic; two can also be considered "established risk-alleles" and one as "likely risk-allele." The prevalence of (likely)-pathogenic variants in the HC cohort was 0.8% (1.3% in breast cancer patients and 1.0% in hereditary nonpolyposis colorectal cancer patients). Here, we provide ACMG adjustment guidelines to classifyCHEK2variants. We hope that this study would be useful for variant classification of other genes with low effect variants.

Filiaciones:
Vargas-Parra, G:
 IDIBELL IGTP IDIBGI, Catalan Inst Oncol, Hereditary Canc Program, Badalona, Spain

 IDIBELL, Program Mol Mech & Expt Therapy Oncol Oncobell, Barcelona, Spain

 Ctr Invest Biomed Red Canc CIBERONC, Madrid, Spain

del Valle, J:
 IDIBELL IGTP IDIBGI, Catalan Inst Oncol, Hereditary Canc Program, Badalona, Spain

 IDIBELL, Program Mol Mech & Expt Therapy Oncol Oncobell, Barcelona, Spain

 Ctr Invest Biomed Red Canc CIBERONC, Madrid, Spain

Rofes, P:
 IDIBELL IGTP IDIBGI, Catalan Inst Oncol, Hereditary Canc Program, Badalona, Spain

 IDIBELL, Program Mol Mech & Expt Therapy Oncol Oncobell, Barcelona, Spain

 Ctr Invest Biomed Red Canc CIBERONC, Madrid, Spain

Gausachs, M:
 IDIBELL IGTP IDIBGI, Catalan Inst Oncol, Hereditary Canc Program, Badalona, Spain

 IDIBELL, Program Mol Mech & Expt Therapy Oncol Oncobell, Barcelona, Spain

 IDIBELL, Catalan Inst Oncol, Dept Med Oncol, Barcelona, Spain

Stradella, A:
 IDIBELL IGTP IDIBGI, Catalan Inst Oncol, Hereditary Canc Program, Badalona, Spain

 IDIBELL, Program Mol Mech & Expt Therapy Oncol Oncobell, Barcelona, Spain

 IDIBELL, Catalan Inst Oncol, Dept Med Oncol, Barcelona, Spain

Moreno-Cabrera, JM:
 IDIBELL IGTP IDIBGI, Catalan Inst Oncol, Hereditary Canc Program, Badalona, Spain

 IDIBELL, Program Mol Mech & Expt Therapy Oncol Oncobell, Barcelona, Spain

 Ctr Invest Biomed Red Canc CIBERONC, Madrid, Spain

Velasco, A:
 IDIBELL IGTP IDIBGI, Catalan Inst Oncol, Hereditary Canc Program, Badalona, Spain

 IDIBELL, Program Mol Mech & Expt Therapy Oncol Oncobell, Barcelona, Spain

 Ctr Invest Biomed Red Canc CIBERONC, Madrid, Spain

Tornero, E:
 IDIBELL IGTP IDIBGI, Catalan Inst Oncol, Hereditary Canc Program, Badalona, Spain

 IDIBELL, Program Mol Mech & Expt Therapy Oncol Oncobell, Barcelona, Spain

 Ctr Invest Biomed Red Canc CIBERONC, Madrid, Spain

Menendez, M:
 IDIBELL IGTP IDIBGI, Catalan Inst Oncol, Hereditary Canc Program, Badalona, Spain

 IDIBELL, Program Mol Mech & Expt Therapy Oncol Oncobell, Barcelona, Spain

 Ctr Invest Biomed Red Canc CIBERONC, Madrid, Spain

Munoz, X:
 IDIBELL IGTP IDIBGI, Catalan Inst Oncol, Hereditary Canc Program, Badalona, Spain

 IDIBELL, Program Mol Mech & Expt Therapy Oncol Oncobell, Barcelona, Spain

 Ctr Invest Biomed Red Canc CIBERONC, Madrid, Spain

Iglesias, S:
 IDIBELL IGTP IDIBGI, Catalan Inst Oncol, Hereditary Canc Program, Badalona, Spain

 IDIBELL, Program Mol Mech & Expt Therapy Oncol Oncobell, Barcelona, Spain

 Ctr Invest Biomed Red Canc CIBERONC, Madrid, Spain

Lopez-Doriga, A:
 Catalan Inst Oncol, Oncol Data Analyt Program ODAP, Barcelona, Spain

 Consortium Biomed Res Epidemiol & Publ Hlth CIBER, Madrid, Spain

Azuara, D:
 IDIBELL IGTP IDIBGI, Catalan Inst Oncol, Hereditary Canc Program, Badalona, Spain

 IDIBELL, Program Mol Mech & Expt Therapy Oncol Oncobell, Barcelona, Spain

 Ctr Invest Biomed Red Canc CIBERONC, Madrid, Spain

Campos, O:
 IDIBELL IGTP IDIBGI, Catalan Inst Oncol, Hereditary Canc Program, Badalona, Spain

 IDIBELL, Program Mol Mech & Expt Therapy Oncol Oncobell, Barcelona, Spain

 Ctr Invest Biomed Red Canc CIBERONC, Madrid, Spain

Cuesta, R:
 IDIBELL IGTP IDIBGI, Catalan Inst Oncol, Hereditary Canc Program, Badalona, Spain

 IDIBELL, Program Mol Mech & Expt Therapy Oncol Oncobell, Barcelona, Spain

 Ctr Invest Biomed Red Canc CIBERONC, Madrid, Spain

Darder, E:
 IDIBELL IGTP IDIBGI, Catalan Inst Oncol, Hereditary Canc Program, Badalona, Spain

 IDIBELL, Program Mol Mech & Expt Therapy Oncol Oncobell, Barcelona, Spain

 Ctr Invest Biomed Red Canc CIBERONC, Madrid, Spain

:
 Inst Germans Trias & Pujol PMPPC IGTP, Programa Med Predict & Personalitzada Canc, Genomes Life GCAT Lab Grp, Badalona, Spain

Gonzalez, S:
 IDIBELL IGTP IDIBGI, Catalan Inst Oncol, Hereditary Canc Program, Badalona, Spain

 IDIBELL, Program Mol Mech & Expt Therapy Oncol Oncobell, Barcelona, Spain

 Ctr Invest Biomed Red Canc CIBERONC, Madrid, Spain

Teule, A:
 IDIBELL IGTP IDIBGI, Catalan Inst Oncol, Hereditary Canc Program, Badalona, Spain

 IDIBELL, Program Mol Mech & Expt Therapy Oncol Oncobell, Barcelona, Spain

 Ctr Invest Biomed Red Canc CIBERONC, Madrid, Spain

Navarro, M:
 IDIBELL IGTP IDIBGI, Catalan Inst Oncol, Hereditary Canc Program, Badalona, Spain

 IDIBELL, Program Mol Mech & Expt Therapy Oncol Oncobell, Barcelona, Spain

 Ctr Invest Biomed Red Canc CIBERONC, Madrid, Spain

Brunet, J:
 IDIBELL IGTP IDIBGI, Catalan Inst Oncol, Hereditary Canc Program, Badalona, Spain

 IDIBELL, Program Mol Mech & Expt Therapy Oncol Oncobell, Barcelona, Spain

 Ctr Invest Biomed Red Canc CIBERONC, Madrid, Spain

 Univ Girona, Sch Med, Dept Med Sci, Girona, Spain

Capella, G:
 IDIBELL IGTP IDIBGI, Catalan Inst Oncol, Hereditary Canc Program, Badalona, Spain

 IDIBELL, Program Mol Mech & Expt Therapy Oncol Oncobell, Barcelona, Spain

 Ctr Invest Biomed Red Canc CIBERONC, Madrid, Spain

Pineda, M:
 IDIBELL IGTP IDIBGI, Catalan Inst Oncol, Hereditary Canc Program, Badalona, Spain

 IDIBELL, Program Mol Mech & Expt Therapy Oncol Oncobell, Barcelona, Spain

 Ctr Invest Biomed Red Canc CIBERONC, Madrid, Spain

Feliubadalo, L:
 IDIBELL IGTP IDIBGI, Catalan Inst Oncol, Hereditary Canc Program, Badalona, Spain

 IDIBELL, Program Mol Mech & Expt Therapy Oncol Oncobell, Barcelona, Spain

 Ctr Invest Biomed Red Canc CIBERONC, Madrid, Spain

Lazaro, C:
 IDIBELL IGTP IDIBGI, Catalan Inst Oncol, Hereditary Canc Program, Badalona, Spain

 IDIBELL, Program Mol Mech & Expt Therapy Oncol Oncobell, Barcelona, Spain

 Ctr Invest Biomed Red Canc CIBERONC, Madrid, Spain
ISSN: 10597794





Human Mutation
Editorial
John Wiley & Sons Inc., 111 RIVER ST, HOBOKEN 07030-5774, NJ USA, Estados Unidos America
Tipo de documento: Article
Volumen: 41 Número: 12
Páginas: 2128-2142
WOS Id: 000578820800001
ID de PubMed: 32906215

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